Desmoplastic ameloblastoma (DA) is one of 6 subtypes and also a rare variant of ameloblastoma. It is not recognized perfectly up to now. Although most of the conventional ameloblastomas can be diagnosed in posterior of the mandible, DA more transpires in anterior of the jaws. Our patient was a 57-year-old man with swelling in the right side of the anterior maxilla. In the medical examination bone expansion was detected with a normal covering mucosa and no discoloration. This paper provides more information about cone beam computed tomography image features of DA.